Case Report

The Journal of the Korean Rheumatism Association 2004; 11(4): 453-456

Published online December 30, 2004

© Korean College of Rheumatology

관절 과가동성 증후군에 동반된 강직성 척추염 1예

윤현정·조석·홍서나·이신석

전남대학교 의과대학 류마티스내과

A Case of Coexistent Benign Joint Hypermobility Syndrome and Ankylosing Spondylitis

Hyun-Jung Yoon, M.D., Seok Jo, M.D., Seo-Na Hong, M.D., Shin-Seok Lee, M.D.

Department of Rheumatology, Chonnam National University Medical School, Gwangju, Korea

Correspondence to : Shin-Seok Lee, M.D.

Abstract

Benign Joint Hypermobility Syndrome (BJHS) is characterized by generalized ligamentous laxity, with associated tendency to recurrent sprain and dislocation. Whereas ankylosing spondylitis (AS) is characterized by ankylosis and loss of mobility of the affected joints by fibrosis and ossification of cartilage and enthesis. The association of these two pathologies is rare. We report on a 18-year old man with a joint hypermobility and laxity as well as accompanying 18-month history of back pain at the lumbar spine, both knee and left buttock pain. At physical examination the patient presented 5 points of Nine-Point Beighton hypermobility score and limitation of movement in the lumbar spine due to back pain. Magnetic resonance imaging of the pelvis showed bilateral sacroiliitis and erythrocyte sedimentation rate (ESR) and C-reactive protein (CRP) were elevated and HLA B27 was positive. Transthoracic echocardiography and opthalmologic examination excluded other cause of joint hypermobility. We diagnosed co-existent BJHS and AS.

Keywords Benign joint hypermobility syndrome, Ankylosing spondylitis

Article

Case Report

The Journal of the Korean Rheumatism Association 2004; 11(4): 453-456

Published online December 30, 2004

Copyright © Korean College of Rheumatology.

관절 과가동성 증후군에 동반된 강직성 척추염 1예

윤현정·조석·홍서나·이신석

전남대학교 의과대학 류마티스내과

A Case of Coexistent Benign Joint Hypermobility Syndrome and Ankylosing Spondylitis

Hyun-Jung Yoon, M.D., Seok Jo, M.D., Seo-Na Hong, M.D., Shin-Seok Lee, M.D.

Department of Rheumatology, Chonnam National University Medical School, Gwangju, Korea

Correspondence to:Shin-Seok Lee, M.D.

Abstract

Benign Joint Hypermobility Syndrome (BJHS) is characterized by generalized ligamentous laxity, with associated tendency to recurrent sprain and dislocation. Whereas ankylosing spondylitis (AS) is characterized by ankylosis and loss of mobility of the affected joints by fibrosis and ossification of cartilage and enthesis. The association of these two pathologies is rare. We report on a 18-year old man with a joint hypermobility and laxity as well as accompanying 18-month history of back pain at the lumbar spine, both knee and left buttock pain. At physical examination the patient presented 5 points of Nine-Point Beighton hypermobility score and limitation of movement in the lumbar spine due to back pain. Magnetic resonance imaging of the pelvis showed bilateral sacroiliitis and erythrocyte sedimentation rate (ESR) and C-reactive protein (CRP) were elevated and HLA B27 was positive. Transthoracic echocardiography and opthalmologic examination excluded other cause of joint hypermobility. We diagnosed co-existent BJHS and AS.

Keywords: Benign joint hypermobility syndrome, Ankylosing spondylitis

JRD
Jan 01, 2025 Vol.32 No.1, pp. 1~7
COVER PICTURE
Cumulative growth of rheumatology members and specialists (1980~2024). Cumulative distribution of the number of the (A) Korean College of Rheumatology members and (B) rheumatology specialists. (J Rheum Dis 2025;32:63-65)

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